- Abstract viewed - 2042 times
- PDF downloaded - 872 times
Affiliations
Lenka Kučerová
Department of Gastroenterology, University Hospital Bohunice, Brno
Jiří Dolina
Department of Gastroenterology, University Hospital Bohunice, Brno
Milan Dastych
Department of Gastroenterology, University Hospital Bohunice, Brno
Daniel Bartušek
Department of Radiology, University Hospital Bohunice, Brno
Tomáš Honzík
Department of Pediatrics and Adolescent Medicine, General University Hospital, Prague
Jan Mazanec
Department of Pathology, University Hospital Bohunice, Brno
Lumír Kunovský
Department of Gastroenterology, University Hospital Bohunice, Brno; Department of Surgery, University Hospital Bohunice, Brno, Czech Republic
How to Cite
Mitochondrial Neurogastrointestinal Encephalomyopathy Imitating Crohn’s Disease: A Rare Cause of Malnutrition
- Lenka Kučerová ,
- Jiří Dolina ,
- Milan Dastych ,
- Daniel Bartušek ,
- Tomáš Honzík ,
- Jan Mazanec ,
- Lumír Kunovský
Vol 27 No 3: September 2018
Section: Case Reports
Pages: 321-325
Abstract
Mitochondrial neurogastrointestinal encephalomyopathy (MNGIE) is a rare autosomal recessive disease caused by a mutation in the TYMP gene encoding thymidine phosphorylase. MNGIE causes gastrointestinal and neurological symptoms in homozygous individuals and is often misdiagnosed as anorexia nervosa, inflammatory bowel disease, or celiac disease. We present the case of a 26-year-old female with MNGIE, who was initially diagnosed with anorexia nervosa and Crohn’s disease. The diagnosis of MNGIE was established by biochemical confirmation of elevated serum and urine thymidine and deoxyuridine levels after multiple examinations and several years of disease progression and ineffective treatment. Subsequent molecular genetic testing demonstrated a homozygous TYMP gene mutation. MNGIE should be considered in patients with unexplained malnutrition, intestinal dysmotility, and atypical neurological symptoms.